Language Development From Early Childhood to Adolescence in Youths With Fragile X Syndrome.
Language Development From Early Childhood to Adolescence in Youths With Fragile X Syndrome.
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DOI：
10.1044/2020_jslhr-20-00198
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发表时间：
2020-11-13
期刊：
影响因子：
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通讯作者：
Warren SF
中科院分区：
文献类型：
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作者：
Brady NC;Fleming K;Bredin-Oja SL;Fielding-Gebhardt H;Warren SF
本研究旨在探讨脆性X综合征（FXS）患者从幼儿期到青春期的语言发育以及母亲反应性对语言发育的影响。我们对55名患有FXS的青少年（44名男性，11名女性）的语言发展进行了纵向分析。数据收集的年龄跨度为11-216个月。我们用标准化测试来测量表达性和接受性词汇。不同的单词和话语的平均长度的数量从语言样本分析的母亲和孩子的互动。我们还测量了语言样本和儿童非语言智商过程中产生的母亲评论（反应性指标）。生长模型表明，不同词的数量和接受性词汇的比率与母亲的评论有关。平均长度的话语并没有随着时间的推移显着变化。用标准化测试测量的表达性词汇增长，但增长与母亲的评论无关。非语言智商与10岁时的所有语言结果以及词汇量随时间的变化有关。视觉分析表明，女孩在标准化考试中取得最高分;然而，从语言样本分析得出的衡量标准似乎对男孩和女孩相似。仅男孩的语言模型与总样本模型相似，10岁时某些结果的得分较低。大多数患有FXS的青少年持续性语言障碍的结果表明，除了响应环境外，还需要持续的，有针对性的干预措施，旨在改善语言制作。 https://doi.org/10.23641/asha.13022825
The aim of this study was to investigate language growth in individuals with fragile X syndrome (FXS) from early childhood to adolescence and the influence of maternal responsivity on language growth. We conducted a longitudinal analysis of language development in 55 youths (44 males, 11 females) with FXS. Data collection spanned the ages of 11–216 months. We measured expressive and receptive vocabulary with standardized tests. The number of different words and mean length of utterance were obtained from language sample analyses of mother–child interactions. We also measured maternal comments (responsivity indicator) produced during the language samples and child nonverbal IQ. Growth models indicated that rates of number of different words and receptive vocabulary were related to maternal commenting. Mean length of utterance did not change significantly over time. Expressive vocabulary measured with a standardized test grew, but the growth was not related to maternal commenting. Nonverbal IQ was related to all language outcomes at age of 10 years and to changes over time in vocabulary. Visual analysis indicated that the highest scores on standardized tests were produced by girls; however, measures derived from language sample analyses appeared similar for boys and girls. Language models for boys only were similar to the total sample models with lower scores at age of 10 years for some outcomes. Results of persistent language impairments for most youths with FXS suggest the need for continued, focused interventions aimed at improved language productions in addition to a responsive environment. https://doi.org/10.23641/asha.13022825