Orbital infarction syndrome after multiple percutaneous sclerotherapy sessions for facial low-flow vascular malformation: A case report and literature review
Orbital infarction syndrome after multiple percutaneous sclerotherapy sessions for facial low-flow vascular malformation: A case report and literature review
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DOI：
10.4103/0301-4738.191508
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发表时间：
2016-08-01
影响因子：
3.1
通讯作者：
Liang, I-Chia
中科院分区：
文献类型：
--
作者：
Sio, Weng Sut;Lee, Shwu-Huey;Liang, I-Chia
面部血管畸形（VMs）硬化治疗后视力丧失是一种罕见但有害的并发症。在此，我们报告一例11岁的男孩，在接受第14次硬化治疗（经皮病灶内注射十四烷基硫酸钠）后，右眼出现急性上睑下垂、眼麻痹和失明。计算机断层血管造影显示右眼动脉、眼上静脉或眼外肌没有增强。他表现出眼眶梗死综合征的特征：明显的前后段缺血征象和眼外肌动脉血流中断。4个月后上睑下垂和眼球运动改善；然而，他一直失明，最终患上了肺结核。因此，面部vm的硬化治疗，即使不累及眼眶，也可能导致严重的眼部和眼眶并发症。
Vision loss following sclerotherapy for facial vascular malformations (VMs) is a rare but detrimental complication. Here, we report a case of an 11-year-old boy with acute onset blepharoptosis, ophthalmoplegia, and blindness in his right eye after the 14th sclerotherapy session (percutaneous intralesional injection of sodium tetradecyl sulfate) for a right facial low-flow VM without orbital involvement. Computed tomography angiography revealed no contrast enhancement in the right ophthalmic artery, superior ophthalmic vein, or extraocular muscles. He presented with the hallmarks of orbital infarction syndrome: Clear signs of anterior and posterior segment ischemia and disrupted arterial flow to the extraocular muscles. His blepharoptosis and eye movement improved 4 months later; however, he remained blind, and phthisis bulbi developed eventually. Thus, sclerotherapy for facial VM-even without orbital involvement-may result in severe ocular and orbital complications.